PT - JOURNAL ARTICLE AU - Ayed, Abdullah AU - Alwadai, Raed I. AU - Rezigalla, Assad A. TI - A rare case of a horseshoe kidney with a single left-sided ureter presented with recurrent urinary tract infection AID - 10.15537/smj.2025.46.1.20240826 DP - 2025 Jan 01 TA - Saudi Medical Journal PG - 102--106 VI - 46 IP - 1 4099 - http://smj.org.sa/content/46/1/102.short 4100 - http://smj.org.sa/content/46/1/102.full SO - Saudi Med J2025 Jan 01; 46 AB - The horseshoe kidney (HSK) is a common renal abnormality mostly asymptomatic. This may be linked to chromosomal and organ anomalies. A 27-year-old male patient presented with mild recurrent lower abdominal pain associated with dysuria. No history of renal disease. Laboratory investigations revealed red blood cells (RBC), white blood cells (WBC), and bacterial growth in the urine. A CT urogram showed an HSK with a unilateral left-sided ureter. The patient was diagnosed with a urinary tract infection (UTI) and managed with regular follow-up. This report describes a rare case of an HSK with a unilateral left-sided, typically implanted ureter and highlights the radiological findings and management. Asymptomatic HSKs may present with or without associated anomalies. UTI is a common asymptomatic presentation. An HSK with a unilateral left-sided normally implanted ureter is rare. The present case of HSK was associated with recurrent UTI, which was managed accordingly.